IP Library Granted Patent US 12,599,594
Granted Patent B2
US 12,599,594 · App. 18/199,120 · Granted Apr 14, 2026

Treatment of Fabry disease in ERT-naïve and ERT-experienced patients

Inventor: Jeff Castelli (New Hope, PA)
Assignee: Amicus Therapeutics, Inc.
A61K31/445A61K31/45A61K31/7008
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Quick Facts
Patent No.
US 12,599,594
App. No.
18/199,120
Granted
Apr 14, 2026
Kind
B2
Abstract

Provided are dosing regimens for the treatment of Fabry disease in a patient. Certain methods relate to the treatment of ERT-experienced or ERT-naïve Fabry patients. Certain methods comprise administering to the patient about 123 mg free base equivalent of migalastat for improving left ventricular mass and/or improving podocyte globotriaosylceramide.

Claims (12)

1 . A method of reducing left ventricular mass index (LVMi) in an enzyme replacement therapy (ERT)-experienced human patient having Fabry disease, the method comprising administering to the patient a formulation comprising an effective amount of 1-deoxygalactonojirimycin or salt thereof every other day, wherein the effective amount is about 123 mg free base equivalent (FBE) and wherein the patient has left ventricular hypertrophy (LVH) prior to initiating administration of the 1-deoxygalactonojirimycin or salt thereof.

2 . The method of claim 1 , wherein the 1-deoxygalactonojirimycin or salt thereof enhances-galactosidase A activity.

3 . The method of claim 1 , wherein the patient is administered about 123 mg of 1-deoxygalactonojirimycin every other day.

4 . The method of claim 1 , wherein the patient is administered about 150 mg of migalastat hydrochloride every other day.

5 . The method of claim 1 , wherein the formulation comprises an oral dosage form.

6 . The method of claim 5 , wherein the oral dosage form comprises a tablet, a capsule or a solution.

7 . A method of reducing podocyte globotriaosylceramide (GL-3) in an enzyme replacement therapy (ERT)-experienced human patient having Fabry disease, the method comprising administering to the patient a formulation comprising an effective amount of 1-deoxygalactonojirimycin or salt thereof every other day, wherein the effective amount is about 123 mg free base equivalent (FBE).

8 . The method of claim 7 , wherein the 1-deoxygalactonojirimycin or salt thereof enhances-galactosidase A activity.

9 . The method of claim 7 , wherein the patient is administered about 123 mg of 1-deoxygalactonojirimycin every other day.

10 . The method of claim 7 , wherein the patient is administered about 150 mg of migalastat hydrochloride every other day.

11 . The method of claim 7 , wherein the formulation comprises an oral dosage form.

12 . The method of claim 11 , wherein the oral dosage form comprises a tablet, a capsule or a solution.

Assignments (3)
SECURITY INTEREST Recorded Apr 27, 2026
From: BIOMARIN PHARMACEUTICAL INC.; AMICUS THERAPEUTICS, INC.
To: CITIBANK, N.A., AS COLLATERAL AGENT
Reel/Frame 075493/0968 →
RELEASE OF SECURITY INTEREST Recorded Apr 27, 2026
From: WILMINGTON TRUST, NATIONAL ASSOCIATION
To: AMICUS THERAPEUTICS, INC.
Reel/Frame 075494/0030 →
SECURITY INTEREST Recorded Oct 6, 2023
From: AMICUS THERAPEUTICS, INC.
To: WILMINGTON TRUST, NATIONAL ASSOCIATION
Reel/Frame 065177/0196 →
Continuity (3)
Continuation 16318905
Continuation 15213920 · Jul 19, 2016
Related Publication 20230321065A1 · Oct 12, 2023
References Cited (3)
Giugliani, R., et al. “A phase 2 study of migalastat hydrochloride in females with Fabry disease: selection of population, safety and pharmacodynamic effects.” Molecular Genetics and Metabolism 109.1 (2013): 86-92. [cited by examiner]
Markham, Anthony. “Migalastat: first global approval.” Drugs 76 (2016): 1147-1152. [cited by examiner]
European Medicines Agency (EMA). Galafold—Assessment Report. International non-proprietary name: migalastat. EMA/272226/2016, Procedure No. EMEA/H/C/004059/0000, Apr. 1, 2016. [cited by applicant]